Case Report: Long-term nutritional and surgical management of short bowel syndrome in a child with Strømme syndrome
Strømme syndrome is an extremely rare autosomal recessive ciliopathy caused by biallelic mutations in CENPF , characterized by microcephaly, ocular abnormalities, and intestinal atresia; intestinal involvement can evolve into short bowel syndrome (SBS), a recognized but infrequently documented complication. We report the case of an infant with genetically confirmed Strømme syndrome, complicated by severe apple-peel jejunoileal atresia that progressed to SBS. After an initial phase of total dependence on parenteral nutrition (PN) and recurrent catheter-related infectious complications, a coordinated, individually tailored care plan combining personalized nutritional strategies with intensive follow-up allowed a gradual transition to partial oral feeding combined with cyclical home PN. Despite the severity of the condition and the prolonged duration of PN, the child achieved catch-up growth (from an initial nadir to the 50th percentile by the latest follow-up) and preserved liver function. To our knowledge, this is the first detailed report of the long-term nutritional rehabilitation and PN-weaning trajectory in a child with genetically confirmed Strømme syndrome complicated by SBS, showing how well-structured, personalized, and integrated home nutritional management can lead to positive outcomes even in this complex and rare setting.
Authors
- Thomas Zoller (ORCID: https://orcid.org/0000-0001-5429-6036)
- Marco Zaffanello (ORCID: https://orcid.org/0000-0002-8659-5505)
- Valentino Bertasi
- Franco Antoniazzi (ORCID: https://orcid.org/0000-0003-1405-1792)
- Angelo Pietrobelli (ORCID: https://orcid.org/0000-0002-9912-3232)
- GIORGIO L. PIACENTINI (ORCID: https://orcid.org/0000-0003-1324-4373)
- Ruggero Lanzafame (ORCID: https://orcid.org/0009-0009-5378-1895)
- Chiara Roncarà
- Maria Pisano
- Marco Caggese
Institutions
- Pennington Biomedical Research Center (US)
- University of Verona (IT)
Publication Details
- Journal
- Frontiers in Pediatrics
- Published
- 2026-11-02
- DOI
- https://doi.org/10.3389/fped.2026.1979082
- Primary Topic
- Clinical Nutrition and Gastroenterology
- Type
- article
- Field-Weighted Citation Impact
- 0.00