Differentiating Sporadic and Familial Adenomatous Polyposis-Associated Congenital Hypertrophy of the Retinal Pigment Epithelium From Congenital Grouped Pigmentation: A Review of Morphologic, Histopathologic, and Multimodal Imaging

Congenital hypertrophy of the retinal pigment epithelium (CHRPE) occurs both as a sporadic finding and as an extraintestinal manifestation of familial adenomatous polyposis (FAP). Congenital grouped pigmentation (CGP, "bear tracks") represents a third distinct entity that may be confused with FAP-associated lesions. Accurate differentiation among these three entities has important clinical implications for appropriate surveillance, counseling, and patient management. Although prior reviews have synthesized the morphologic, histopathologic, and multimodal imaging features of pigmented retinal pigment epithelium (RPE) lesions, subsequent multimodal imaging studies and evolving evidence have refined the distinctions among FAP-associated lesions, sporadic solitary CHRPE, and CGP. This narrative review provides an updated synthesis on the clinical, fundoscopic, optical coherence tomography (OCT), fundus autofluorescence (FAF), OCT angiography (OCTA), and histopathologic features of FAP-associated CHRPE, sporadic solitary CHRPE, and CGP. Key differentiating features of FAP-associated lesions include multiplicity, bilaterality, absence of lacunae, absence of cystoid edema, and presence of pigment epithelial detachments (PEDs). CGP is distinguished by its wedge-shaped (sectorial) distribution pattern, preserved outer retinal architecture on OCT, and retention of normal ellipsoidal pigment granule morphology on histopathology. An evidence-based diagnostic feature comparison framework is proposed to assist clinicians in determining which patients with pigmented RPE lesions warrant genetic evaluation for FAP.

Authors

Publication Details

Journal
Cureus
Published
2026-07-28
DOI
https://doi.org/10.7759/cureus.113498
Primary Topic
Ocular Oncology and Treatments
Type
article
Field-Weighted Citation Impact
0.00
Controls
|||
ALL TIME
JAN
FEB
MAR
APR
MAY
JUN
JUL
AUG
SEP
OCT
article

Differentiating Sporadic and Familial Adenomatous Polyposis-Associated Congenital Hypertrophy of the Retinal Pigment Epithelium From Congenital Grouped Pigmentation: A Review of Morphologic, Histopathologic, and Multimodal Imaging

Gianluca Ramirez, Sean Mahajan, Nikita K Patel, Vasudeva R Samala et al.
Cureus
Ocular Oncology and Treatments
article

Differentiating Sporadic and Familial Adenomatous Polyposis-Associated Congenital Hypertrophy of the Retinal Pigment Epithelium From Congenital Grouped Pigmentation: A Review of Morphologic, Histopathologic, and Multimodal Imaging

Gianluca Ramirez, Sean Mahajan, Nikita K Patel, Vasudeva R Samala, Kiara Machado, Vinitha R Samala, Vikram Sivakumar, Abhiram R Manda
article en

Abstract

Congenital hypertrophy of the retinal pigment epithelium (CHRPE) occurs both as a sporadic finding and as an extraintestinal manifestation of familial adenomatous polyposis (FAP). Congenital grouped pigmentation (CGP, "bear tracks") represents a third distinct entity that may be confused with FAP-associated lesions. Accurate differentiation among these three entities has important clinical implications for appropriate surveillance, counseling, and patient management. Although prior reviews have synthesized the morphologic, histopathologic, and multimodal imaging features of pigmented retinal pigment epithelium (RPE) lesions, subsequent multimodal imaging studies and evolving evidence have refined the distinctions among FAP-associated lesions, sporadic solitary CHRPE, and CGP. This narrative review provides an updated synthesis on the clinical, fundoscopic, optical coherence tomography (OCT), fundus autofluorescence (FAF), OCT angiography (OCTA), and histopathologic features of FAP-associated CHRPE, sporadic solitary CHRPE, and CGP. Key differentiating features of FAP-associated lesions include multiplicity, bilaterality, absence of lacunae, absence of cystoid edema, and presence of pigment epithelial detachments (PEDs). CGP is distinguished by its wedge-shaped (sectorial) distribution pattern, preserved outer retinal architecture on OCT, and retention of normal ellipsoidal pigment granule morphology on histopathology. An evidence-based diagnostic feature comparison framework is proposed to assist clinicians in determining which patients with pigmented RPE lesions warrant genetic evaluation for FAP.

Cureus
Openalex Percentile: Top 6%
Ocular Oncology and Treatments
AI Navigator

Ask Laika to Summarize, Analyze, and Connect papers live on the map.

Summarize Papers & Methodologies

Extract key findings, datasets, and comparative methods across publications.

Benchmark Rankings & Visual Analytics

Rank top research institutions, authors, funders, topics, and journals by Field-Weighted Citation Impact (FWCI) and paper volume with instant charts.

Connect Distant Disciplines

Bridge topological clusters on the map to find hidden collaborative intersections.