Management of Iron Overload in Infants and Toddlers With Diamond–Blackfan Anemia Syndrome: A French–Italian Study

Diamond-Blackfan Anemia Syndrome (DBAS) is a rare congenital anemia often requiring chronic red blood cell transfusions from infancy. Without appropriate chelation, iron overload develops early and may be severe; however, no data are available on chelation in patients under 3 years of age. To address this, we conducted a retrospective, multicenter study collecting data from the French and Italian DBAS national registries. A total of 167 transfused DBAS patients were screened. Of these, 64 (38%) initiated chelation before the age of three (median: 18 months). Indications for chelation were a serum ferritin ≥ 500 ng/mL (median: 1340 ng/mL) and more than 10 transfusions. Deferasirox was the most frequently used chelator (63%), followed by deferoxamine (35%). Chelation was associated with a significant reduction in serum ferritin levels (-11% per year; p < 0.001). At 5-6 years of age, ferritin level was available for 28 patients: 43% had levels < 500 ng/mL, and none exceeded 2000 ng/mL. Liver iron concentration was assessed in 31/64 patients (48%) at a median age of 3.2 years; 45% showed severe overload at first evaluation. Among 22 patients who underwent cardiac magnetic resonance, no myocardial iron overload was detected. These real-world data support the feasibility, tolerability, and effectiveness of chelation in transfusion-dependent DBAS patients under 3 years, allowing prevention of cardiac iron overload. Although derived from DBAS, these findings may inform the management of iron overload in infants and toddlers with other transfusion-dependent anemias and support development of age-specific chelation strategies.

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Journal
American Journal of Hematology
Published
2026-05-11
DOI
https://doi.org/10.1002/ajh.70354
Primary Topic
RNA modifications and cancer
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article
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article

Management of Iron Overload in Infants and Toddlers With Diamond–Blackfan Anemia Syndrome: A French–Italian Study

Anne Sîrvent, Maria Licciardello, Adriana Carando, Nathalie Garnier et al.
American Journal of Hematology
RNA modifications and cancer
article

Management of Iron Overload in Infants and Toddlers With Diamond–Blackfan Anemia Syndrome: A French–Italian Study

Anne Sîrvent, Maria Licciardello, Adriana Carando, Nathalie Garnier, Emanuela Garelli, Elisa Bertoni, F Fagioli, Coralie Mallebranche, Marco Zecca, Thierry Leblanc, Antonella Sau, Arthur Sterin, Marie‐Pierre Castex, Francesca Torchio, Paola Quarello, Nathalie Aladjidi, Isabelle Marie, Lydie M. Da Costa, Baptiste Lecalvez, Benedicte Bruno
article en

Abstract

Diamond-Blackfan Anemia Syndrome (DBAS) is a rare congenital anemia often requiring chronic red blood cell transfusions from infancy. Without appropriate chelation, iron overload develops early and may be severe; however, no data are available on chelation in patients under 3 years of age. To address this, we conducted a retrospective, multicenter study collecting data from the French and Italian DBAS national registries. A total of 167 transfused DBAS patients were screened. Of these, 64 (38%) initiated chelation before the age of three (median: 18 months). Indications for chelation were a serum ferritin ≥ 500 ng/mL (median: 1340 ng/mL) and more than 10 transfusions. Deferasirox was the most frequently used chelator (63%), followed by deferoxamine (35%). Chelation was associated with a significant reduction in serum ferritin levels (-11% per year; p < 0.001). At 5-6 years of age, ferritin level was available for 28 patients: 43% had levels < 500 ng/mL, and none exceeded 2000 ng/mL. Liver iron concentration was assessed in 31/64 patients (48%) at a median age of 3.2 years; 45% showed severe overload at first evaluation. Among 22 patients who underwent cardiac magnetic resonance, no myocardial iron overload was detected. These real-world data support the feasibility, tolerability, and effectiveness of chelation in transfusion-dependent DBAS patients under 3 years, allowing prevention of cardiac iron overload. Although derived from DBAS, these findings may inform the management of iron overload in infants and toddlers with other transfusion-dependent anemias and support development of age-specific chelation strategies.

American Journal of Hematology
Centre National de la Recherche Scientifique (FR), Inserm (FR), Université Paris Cité (FR), Université Paris-Saclay (FR), Institut Gustave Roussy (FR), Saint Louis University Hospital (US), University of Catania (IT), Institut d’Hématologie et d’Oncologie Pédiatrique (FR), Centre de Recherche en Cancérologie et Immunologie Intégrée Nantes Angers (FR), Centre Hospitalier Universitaire de Montpellier (FR), Azienda Socio Sanitaria Territoriale degli Spedali Civili di Brescia (IT), Hôpital Jeanne de Flandre (FR), Ospedale di Santo Spirito (IT), Laboratoire National de Référence (MA), Hôpital Pellegrin (FR), Centre Hospitalier Universitaire d'Angers (FR), Hôpital Robert-Debré (FR), Ospedale Regina Margherita (IT), Hôpital Saint-Louis (FR), Hôpital des Enfants (FR), Policlinico San Matteo Fondazione (IT), Istituti di Ricovero e Cura a Carattere Scientifico (IT), Department of Public Health (US), Hôpital de la Timone (FR), Bicêtre Hospital (FR), Université d'Angers (FR), University of Turin (IT)
Good health and well-being
Openalex Percentile: Top 9%
RNA modifications and cancer
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