Topoisomerase 1-DNA complexes are preferentially recognised by a subset of anti-topoisomerase 1 autoantibodies and their corresponding B cell receptors in systemic sclerosis
OBJECTIVES: Systemic sclerosis (SSc) is a deleterious disease. Its clinical management is complicated by strong interpatient heterogeneity. Progressive organ fibrosis is linked to autoantibodies against topoisomerase 1 (TOP1). Here, we hypothesised that the interaction between anti-TOP1 autoantibodies (ATAs) and TOP1 could influence SSc pathogenesis. TOP1 is a DNA-binding enzyme. Therefore, we studied the effects and functional consequences of TOP1-DNA binding on ATA recognition. METHODS: ATA monoclonal antibodies (ATA mAbs) and ATA-expressing B cell lines were generated from patient-derived TOP1-reactive B cells. Reactivity of monoclonal and polyclonal ATAs towards TOP1 and TOP1-DNA cleavage complexes (TOP1cc) was determined by enzyme-linked immunosorbent assay and mass photometry. Immunostimulatory properties of ATA mAbs in complex with TOP1/TOP1cc were assessed on monocytic THP-1 cells and primary monocytes. The stimulatory effects of TOP1-DNA complexes were tested on ATA-expressing B cells. RESULTS: patients and correlated with ATA levels and interstitial lung disease. These 'TOP1cc-enhanced ATAs' affected the enzymatic function of TOP1 and, in complex with TOP1cc, increased proinflammatory cytokine production by THP-1 cells and primary monocytes. B cells expressing 'TOP1cc-enhanced ATAs' responded strongly to stimulation with TOP1-DNA complexes, whereas additive effects were not observed for B cells expressing 'regular' ATAs. CONCLUSIONS: The differential recognition of TOP1 upon DNA binding by ATAs demonstrates heterogeneity in the ATA B cell response, possibly impacting disease-relevant processes in severe SSc.
Authors
- Marjolein J.A.L. Wetzels (ORCID: https://orcid.org/0000-0003-2501-3230)
- Hans Ulrich Scherer (ORCID: https://orcid.org/0000-0002-5700-5617)
- C. Wortel (ORCID: https://orcid.org/0000-0003-3583-6281)
- Sam Neppelenbroek (ORCID: https://orcid.org/0000-0002-9582-2837)
- Nikki M. Loof (ORCID: https://orcid.org/0009-0008-5642-8627)
- Bart Everts (ORCID: https://orcid.org/0000-0002-3764-5131)
- Robbert Q. Kim (ORCID: https://orcid.org/0000-0003-1834-8673)
- Cynthia M. Fehres (ORCID: https://orcid.org/0000-0001-9020-1591)
- Martina Erbì
- René E. M. Toes
- E.W. Nivine Levarht
- Jeska K. de Vries-Bouwstra
- Danique M.H. van Rijswijck
- Albert J.R. Heck
Institutions
- Utrecht University (NL)
- Leiden University Medical Center (NL)
Publication Details
- Journal
- Annals of the Rheumatic Diseases
- Published
- 2026-04-01
- DOI
- https://doi.org/10.1016/j.ard.2026.03.016
- Primary Topic
- Cancer therapeutics and mechanisms
- Type
- article
- Field-Weighted Citation Impact
- 0.00
Funders
- Health~Holland
- Innovative Health Initiative
- Universiteit Leiden
- ZonMw
- Nederlandse Organisatie voor Wetenschappelijk Onderzoek
- Leids Universitair Medisch Centrum
- Dutch Arthritis Association
- European Research Council