Clinical features of syndromic microphthalmia in two novel RARB variants
Here we describe unrelated Japanese patients with distinct novel heterozygous retinoic acid receptor beta (RARB) gene variants underlying syndromic microphthalmia-12: case 1 with a frameshift variant, c.1205_1206del, had bilateral microphthalmia, corneal opacity, anterior segment dysgenesis, widespread multiorgan anomalies, hypotonia and cognitive impairment; case 2 with a missense variant, c.844G>T had Peters anomaly, extreme microphthalmia, spasticity, profound psychomotor delay and refractory epilepsy. These findings highlight the need for RARB testing.
Authors
- Rika Kosaki (ORCID: https://orcid.org/0000-0002-4367-6129)
- Yoshito Koyanagi (ORCID: https://orcid.org/0000-0001-5559-6305)
- Tomoyo Yoshida
- Hazuki Morikawa-Anzai
- Keiko Matsubara
- Maki Fukami (ORCID: https://orcid.org/0000-0001-9971-4035)
- Yuichi Abe
- Makiko Tominaga
- Sachiko Nishina
Institutions
- Kyushu University (JP)
- SHOWA Medical University Northern Yokohama Hospital (JP)
- National Center For Child Health and Development (JP)
Publication Details
- Journal
- Human Genome Variation
- Published
- 2026-04-06
- DOI
- https://doi.org/10.1038/s41439-026-00345-3
- Primary Topic
- Ocular Disorders and Treatments
- Type
- article
- Field-Weighted Citation Impact
- 0.00