A Novel LDB3 Mutation Identified in Patients with Late-Onset Myofibrillar Myopathy
Objective: Inherited myopathies are a diverse group of genetic muscle disorders characterized by muscle weakness and dysfunction resulting from mutations in genes with a wide range of biological functions. This study was performed to elucidate genetic causes in a large family with late-onset myofibrillar myopathy.Methods: Whole-exome sequencing was first applied to the proband, and then subsequent filtering process and in silico analysis was performed to determine causative mutation.Results: This study identified an unreported likely pathogenic mutation, p.Met160Ile, in the LIM domain binding 3 (LDB3) gene. This missense mutation showed complete cosegregation with affected individuals and was located at an evolutionarily well-conserved site. Several in silico analyses, along with simulations of three-dimensional structural changes in the mutant protein, predicted its potential pathogenicity.Conclusion: These findings expand the current understanding of the genetic basis of inherited myopathy and underscore the importance of comprehensive genetic analysis in clinical practice.
Authors
- Ah Jin Lee
- Soo Hyun Nam (ORCID: https://orcid.org/0000-0003-4421-1793)
- Nasrin Tamanna
- Ki Wha Chung
- Byung-Ok Choi
Institutions
- Kongju National University (KR)
- Samsung Medical Center (KR)
- Sungkyunkwan University (KR)
Publication Details
- Journal
- Journal of Electrodiagnosis and Neuromuscular Diseases
- Published
- 2025-12-31
- DOI
- https://doi.org/10.18214/jend.2025.00031
- Primary Topic
- Cardiomyopathy and Myosin Studies
- Type
- article
- Field-Weighted Citation Impact
- 0.00
Funders
- National Research Foundation
- Ministry of Science and ICT, South Korea