Cartwheel cataract, a specific sign of PAX6-related aniridia
A 35-year-old man, monitored for congenital aniridia, exhibited progressive visual loss and worsening of photophobia over 3 years.Next generation sequencing (NGS) identified a pathogenic heterozygous nonsense variant in PAX6.In addition to the ocular signs of the disease-nystagmus, ptosis, limbal insufficiency, iris hypoplasia, medically treated glaucoma, and foveal hypoplasia-examination revealed a peculiar, white, cartwheel cataract in both eyes, indicated on swept-source optical coherence tomography by hyperreflective posterior layers in the lens (Figures 1, A andB and2, A andB).Congenital aniridia is commonly associated with small congenital anterior subcapsular cataracts, present from birth, which rarely require surgery. 1 Posterior subcapsular cartwheel cataracts, instead, develop progressively in adulthood and can further worsen the vision.This unusual type of cataract, seen in association with congenital aniridia, is highly specific of a causal PAX6 gene anomaly.The patient was operated on, and his vision came back to its baseline.
Authors
- Alejandra Daruich (ORCID: https://orcid.org/0000-0001-7907-4325)
- Sophie Valleix (ORCID: https://orcid.org/0000-0002-4812-7102)
- Matthieu P. Robert (ORCID: https://orcid.org/0000-0003-3353-8117)
- Dominique Brémond‐Gignac (ORCID: https://orcid.org/0000-0002-3563-5482)
Institutions
- Hôpital Necker-Enfants Malades (FR)
- Institut Necker Enfants Malades (FR)
- Hôpital Cochin (FR)
Publication Details
- Journal
- Journal of Cataract & Refractive Surgery
- Published
- 2025-11-12
- DOI
- https://doi.org/10.1097/j.jcrs.0000000000001826
- Primary Topic
- Developmental Biology and Gene Regulation
- Type
- article
- Field-Weighted Citation Impact
- 0.00