Calmodulin enhancement of mitochondrial calcium uniporter function in isolated mitochondria
Mitochondrial calcium (Ca<sup>2+</sup>) uptake and factors that regulate this process have been an area of immense interest given the roles in cellular energetics. Here, we have investigated the ability of the Ca<sup>2+</sup> sensing protein Calmodulin (CaM) to modify the function of the Mitochondrial Ca<sup>2+</sup> Uniporter (MCU). Our data leveraged recombinantly produced CaM and mitochondria isolated from healthy and MCU impaired/diseased mice (Barth syndrome model). We found CaM enhanced Ca<sup>2+</sup> uptake in both the absence and presence of CaMKII inhibition (KN93 as well as AIP). Mitochondria lacking function MCU (Barth syndrome model) validated that MCU was responsible for Ca<sup>2+</sup> uptake in our experiments. Control experiments demonstrate that the observed CaM enhancement does not arise from CaM Ca<sup>2+</sup> buffering. Fitting the Ca<sup>2+</sup>fluorescence data supported a monophasic decay process where the presence of CaM yielded enhanced kinetic rates of Ca<sup>2+</sup> uptake. This CaM enhancement effect persisted in the presence of PTP impairment (cyclosporin), and subtle modification to the CaM protein sequence (D131E) revealed that an intact CaM-C domain Ca<sup>2+</sup> binding was required for enhancement of MCU function.
Authors
- Alexander Nickel (ORCID: https://orcid.org/0000-0002-2562-0439)
- Anton Xu
- Vasco Sequeira (ORCID: https://orcid.org/0000-0002-9192-7674)
- Michael Kohlhaas (ORCID: https://orcid.org/0000-0001-6132-6037)
- Christoph Maack (ORCID: https://orcid.org/0000-0003-3694-4559)
- Katharina J. Ermer
- Christopher N. Johnson (ORCID: https://orcid.org/0000-0001-8618-9729)
- Sara A. Garcia (ORCID: https://orcid.org/0000-0002-6906-7436)
- Anne Neumaier
- Luzia Enzner
Institutions
- University of Würzburg (DE)
- Universitätsklinikum Würzburg (DE)
- Mississippi State University (US)
Publication Details
- Journal
- Cell Calcium
- Published
- 2025-07-19
- DOI
- https://doi.org/10.1016/j.ceca.2025.103056
- Primary Topic
- Mitochondrial Function and Pathology
- Type
- article
- Field-Weighted Citation Impact
- 0.00
Funders
- American Heart Association
- National Institute of General Medical Sciences