Systematic analysis of nonsense variants uncovers peptide release rate as a novel modifier of nonsense-mediated mRNA decay

The phenotypic impact of nonsense variants is determined by nonsense-mediated mRNA decay (NMD), which degrades transcripts with premature termination codons (PTCs). Despite the clinical importance of nonsense variants, transcript-specific and context-dependent variations in NMD activity remain poorly understood. Here, we show that the amino acid preceding the PTC strongly influences NMD activity. Glycine codons promote robust NMD efficiency and show striking enrichment before PTCs but are depleted before normal termination codons. Glycine-PTC enrichment is particularly pronounced in genes tolerant to loss-of-function variants, suggesting efficient elimination of truncated proteins from nonessential genes. We further demonstrate that the peptide release rate during translation termination is an important determinant of NMD activity. We propose a "window of opportunity" model where translation termination kinetics modulate NMD activity. By revealing how sequence context shapes NMD activity through translation termination dynamics, our findings provide a mechanistic framework for improved clinical interpretation of nonsense variants.

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Publication Details

Journal
Cell Genomics
Published
2025-05-19
DOI
https://doi.org/10.1016/j.xgen.2025.100882
Citations
6
Primary Topic
RNA and protein synthesis mechanisms
Type
article
Field-Weighted Citation Impact
4.84

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article

Systematic analysis of nonsense variants uncovers peptide release rate as a novel modifier of nonsense-mediated mRNA decay

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Cell Genomics
RNA and protein synthesis mechanisms
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article

Systematic analysis of nonsense variants uncovers peptide release rate as a novel modifier of nonsense-mediated mRNA decay

Mlana Lore, Michael A. Cortázar, Nikita Biziaev, Jay R. Hesselberth, Divya Kolakada, Elena Alkalaeva, Sujatha Jagannathan, Zeynep Coban‐Akdemir, Marcin Piotr Sajek, Alexey Shuvalov, Neelanjan Mukherjee, Rui Fu, Amy E. Campbell
article en
6 citations

Abstract

The phenotypic impact of nonsense variants is determined by nonsense-mediated mRNA decay (NMD), which degrades transcripts with premature termination codons (PTCs). Despite the clinical importance of nonsense variants, transcript-specific and context-dependent variations in NMD activity remain poorly understood. Here, we show that the amino acid preceding the PTC strongly influences NMD activity. Glycine codons promote robust NMD efficiency and show striking enrichment before PTCs but are depleted before normal termination codons. Glycine-PTC enrichment is particularly pronounced in genes tolerant to loss-of-function variants, suggesting efficient elimination of truncated proteins from nonessential genes. We further demonstrate that the peptide release rate during translation termination is an important determinant of NMD activity. We propose a "window of opportunity" model where translation termination kinetics modulate NMD activity. By revealing how sequence context shapes NMD activity through translation termination dynamics, our findings provide a mechanistic framework for improved clinical interpretation of nonsense variants.

Cell GenomicsVol. 5(7)
Engelhardt Institute of Molecular Biology (RU), University of Colorado Anschutz Medical Campus (US), The University of Texas Health Science Center at Houston (US)
American Heart Association, Narodowa Agencja Wymiany Akademickiej
Zero hunger
Openalex Percentile: Top 5%
RNA and protein synthesis mechanisms
4.84
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