Hermansky-Pudlak syndrome (HPS): a rare genetic interstitial lung disease

Hermansky-Pudlak syndrome pulmonary fibrosis (HPS-PF) is a rare cause of genetic interstitial lung disease (ILD). A man in his 40s who has oculocutaneous albinism (OCA) since birth presented with respiratory failure to the intensive care department. On further evaluation, high-resolution CT was suggestive of non-specific interstitial pneumonia (NSIP). In view of the early age of presentation of ILD and OCA, genetic testing was done, which confirmed the diagnosis of HPS. He was treated with oxygen, steroids and antifibrotics. Lung transplantation is the definitive treatment option, and he is being referred for the same.

Authors

Institutions

Publication Details

Journal
BMJ Case Reports
Published
2025-04-01
DOI
https://doi.org/10.1136/bcr-2025-265086
Primary Topic
melanin and skin pigmentation
Type
article
Field-Weighted Citation Impact
0.00
Controls
|||
ALL TIME
JAN
FEB
MAR
APR
MAY
JUN
JUL
AUG
SEP
OCT
article

Hermansky-Pudlak syndrome (HPS): a rare genetic interstitial lung disease

Kavitha Venkatnarayan, Chitra Veluthat, Priya Ramachandran, Subrata Ghosh
BMJ Case Reports
melanin and skin pigmentation
article

Hermansky-Pudlak syndrome (HPS): a rare genetic interstitial lung disease

Kavitha Venkatnarayan, Chitra Veluthat, Priya Ramachandran, Subrata Ghosh
article en

Abstract

Hermansky-Pudlak syndrome pulmonary fibrosis (HPS-PF) is a rare cause of genetic interstitial lung disease (ILD). A man in his 40s who has oculocutaneous albinism (OCA) since birth presented with respiratory failure to the intensive care department. On further evaluation, high-resolution CT was suggestive of non-specific interstitial pneumonia (NSIP). In view of the early age of presentation of ILD and OCA, genetic testing was done, which confirmed the diagnosis of HPS. He was treated with oxygen, steroids and antifibrotics. Lung transplantation is the definitive treatment option, and he is being referred for the same.

BMJ Case ReportsVol. 18(4)
St. John's National Academy of Health Sciences (IN)
Good health and well-being
Openalex Percentile: Top 92%
melanin and skin pigmentation
AI Navigator

Ask Laika to Summarize, Analyze, and Connect papers live on the map.

Summarize Papers & Methodologies

Extract key findings, datasets, and comparative methods across publications.

Benchmark Rankings & Visual Analytics

Rank top research institutions, authors, funders, topics, and journals by Field-Weighted Citation Impact (FWCI) and paper volume with instant charts.

Connect Distant Disciplines

Bridge topological clusters on the map to find hidden collaborative intersections.