Further evidence of biallelic NAV3 variants associated with recessive neurodevelopmental disorder with dysmorphism, developmental delay, intellectual disability, and behavioral abnormalities

Neuron navigators (NAVs) are cytoskeleton-associated proteins well known for their role in axonal guidance, neuronal migration, and neurite growth necessary for neurodevelopment. Neuron navigator 3 (NAV3) is one of the three NAV proteins highly expressed in the embryonic and adult brain. However, the role of the NAV3 gene in human disease is not well-studied. Recently, five bi-allelic and three mono-allelic variants in NAV3 were reported in 12 individuals from eight unrelated families with neurodevelopmental disorder (NDD). Here, we report five patients from three unrelated consanguineous families segregating autosomal recessive NDD. Patients have symptoms of dysmorphism, intellectual disability, developmental delay, and behavioral abnormalities. Exome sequencing (ES) was performed on two affected individuals from one large family, and one affected individual from each of the other two families. ES revealed two homozygous nonsense c.6325C > T; p.(Gln2109Ter) and c.6577C > T; p.(Arg2193Ter) and a homozygous splice site (c.243 + 1G > T) variants in the NAV3 (NM_001024383.2). Analysis of single-cell sequencing datasets from embryonic and young adult human brains revealed that NAV3 is highly expressed in the excitatory neurons, inhibitory neurons, and microglia, consistent with its role in neurodevelopment. In conclusion, in this study, we further validate biallelic protein truncating variants in NAV3 as a cause of NDD, expanding the spectrum of pathogenic variants in this newly discovered NDD gene.

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Journal
Human Genetics
Published
2024-12-21
DOI
https://doi.org/10.1007/s00439-024-02718-6
Citations
3
Primary Topic
Genomics and Rare Diseases
Type
article
Field-Weighted Citation Impact
1.65

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article

Further evidence of biallelic NAV3 variants associated with recessive neurodevelopmental disorder with dysmorphism, developmental delay, intellectual disability, and behavioral abnormalities

Zafar Iqbal, Selinda Mascarenhas, Saranya Balachandran, Asmat Ali et al.
3 citations
Human Genetics
Genomics and Rare Diseases
1.65
article

Further evidence of biallelic NAV3 variants associated with recessive neurodevelopmental disorder with dysmorphism, developmental delay, intellectual disability, and behavioral abnormalities

Zafar Iqbal, Selinda Mascarenhas, Saranya Balachandran, Asmat Ali, Sajid Malik, Anju Shukla, Periyasamy Radhakrishnan, Syed M. Ijlal Haider, Jelena Pozojevic, Malte Spielmann, Kristian Händler, Ambrin Fatima, Mohsen Ghofrani, Mathias Toft, Nathalie Kruse, Vaishnavi Ashok Badiger, Azmatullah, Sohana Nadeem Hashmi, Naseebullah Kakar
article en
3 citations

Abstract

Neuron navigators (NAVs) are cytoskeleton-associated proteins well known for their role in axonal guidance, neuronal migration, and neurite growth necessary for neurodevelopment. Neuron navigator 3 (NAV3) is one of the three NAV proteins highly expressed in the embryonic and adult brain. However, the role of the NAV3 gene in human disease is not well-studied. Recently, five bi-allelic and three mono-allelic variants in NAV3 were reported in 12 individuals from eight unrelated families with neurodevelopmental disorder (NDD). Here, we report five patients from three unrelated consanguineous families segregating autosomal recessive NDD. Patients have symptoms of dysmorphism, intellectual disability, developmental delay, and behavioral abnormalities. Exome sequencing (ES) was performed on two affected individuals from one large family, and one affected individual from each of the other two families. ES revealed two homozygous nonsense c.6325C > T; p.(Gln2109Ter) and c.6577C > T; p.(Arg2193Ter) and a homozygous splice site (c.243 + 1G > T) variants in the NAV3 (NM_001024383.2). Analysis of single-cell sequencing datasets from embryonic and young adult human brains revealed that NAV3 is highly expressed in the excitatory neurons, inhibitory neurons, and microglia, consistent with its role in neurodevelopment. In conclusion, in this study, we further validate biallelic protein truncating variants in NAV3 as a cause of NDD, expanding the spectrum of pathogenic variants in this newly discovered NDD gene.

Human GeneticsVol. 144(1)
Aga Khan University (PK), Quaid-i-Azam University (PK), Oslo University Hospital (NO), Balochistan University of Information Technology, Engineering and Management Sciences (PK), Manipal Academy of Higher Education (IN), University of Oslo (NO), Universitäres Kinderwunschzentrum Lübeck (DE), University Hospital Schleswig-Holstein (DE), Kasturba Medical College, Manipal (IN), University of Lübeck (DE)
Alexander von Humboldt-Stiftung, Wellcome Trust, Department of Biotechnology, Ministry of Science and Technology, India, Universität zu Lübeck, The Wellcome Trust DBT India Alliance, Helse Sør-Øst RHF
Openalex Percentile: Top 14%
Genomics and Rare Diseases
1.65
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