Opsoclonus-myoclonus-ataxia syndrome associated with bacterial urinary tract infection

Opsoclonus-myoclonus-ataxia syndrome (OMAS) is a rare acquired neurological disorder characterized by opsoclonus, focal or diffuse myoclonus, truncal instability and associated other cerebellar signs and ataxia. While predominantly affecting children, it can rarely manifest in adults and could be associated with infections, paraneoplastic syndrome, drugs or other neurological disorders. We present a case of an elderly gentleman presenting with OMAS associated with a culture-positive urinary tract infection with <i>Escherichia coli</i>, successfully treated with antibiotics and immunoglobulins resulting in significant recovery.